Frontier in Medical & Health Research
DIAGNOSTIC AND THERAPEUTIC CHALLENGES OF INFANTILE SCIMITAR SYNDROME IN A LOWER-MIDDLE INCOME COUNTRY: A CASE SERIES FROM PAKISTAN
pdf

Keywords

Scimitar syndrome; congenital heart disease; Baffle repair; Pneumonectomy; Pakistan.

How to Cite

DIAGNOSTIC AND THERAPEUTIC CHALLENGES OF INFANTILE SCIMITAR SYNDROME IN A LOWER-MIDDLE INCOME COUNTRY: A CASE SERIES FROM PAKISTAN. (2026). Frontier in Medical and Health Research, 4(6), 3558-3566. https://fmhr.net/index.php/fmhr/article/view/3330

Abstract

Background: Infantile Scimitar syndrome (SS) is a rare, severe congenital anomaly involving anomalous right pulmonary venous drainage into the inferior vena cava (IVC). It poses significant diagnostic and management challenges in lower middle-income countries (LMICs) due to symptomatic overlap with endemic diseases.

Case Series: This series details three distinct presentations of infantile SS in Pakistan: Case 1: A 7-month-old female, initially misdiagnosed and treated empirically for pulmonary tuberculosis, was diagnosed with SS and an atrial septal defect (ASD). She underwent a successful intra-atrial pericardial patch baffle (Roger Mee procedure) at age two, demonstrating favorable long-term survival (>10 years). Case 2: A male neonate presented with severe persistent pulmonary hypertension (PPHN) and was diagnosed with SS associated with a rare horseshoe lung anomaly. Due to delayed treatment and parental refusal of timely admission, the patient clinically deteriorated and died at seven months. Case 3: A preterm male neonate presenting with dextroposition, severe right lung hypoplasia, and pulmonary sequestration underwent a successful life-saving right pneumonectomy on the 22nd day of life and was stabilized. Conclusion: Infantile SS exhibits high clinical variability and carries a poor prognosis if treatment is delayed. Advanced multimodality imaging is vital to avoid critical misdiagnoses, and early, tailored surgical interventions ranging from baffle repair to pneumonectomy are essential for survival.

pdf